Artigo Revisado por pares

Paraneoplastic “stiff person syndrome” with metastatic adenocarcinoma and anti-Ri antibodies

2004; Lippincott Williams & Wilkins; Volume: 62; Issue: 8 Linguagem: Inglês

10.1212/01.wnl.0000123694.64121.d5

ISSN

1526-632X

Autores

Dominick J. H. McCabe, Nicholas C. Turner, Debra T. Chao, Alexander Leff, Norman A. Gregson, Howard John Womersley, I. Tong Mak, G D Perkin, Anthony H.V. Schapira,

Tópico(s)

Glycogen Storage Diseases and Myoclonus

Resumo

A 43-year-old woman presented with clinical and electrophysiologic features of stiff person syndrome (SPS), without abdominal or lumbar paraspinal muscle involvement. Investigations revealed metastatic adenocarcinoma of the lung with positive anti-Ri antibodies. Her clinical condition improved with diazepam, baclofen, tizanidine, and palliative chemotherapy. Screening for an underlying malignancy and anti-Ri antibodies should be considered in patients with SPS when clinical presentation is atypical.

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