Artigo Revisado por pares

Prenatal diagnosis of Batten's disease

1996; Elsevier BV; Volume: 347; Issue: 9007 Linguagem: Inglês

10.1016/s0140-6736(96)90148-8

ISSN

1474-547X

Autores

Patricia B. Munroe, Hannah M. Mitchison, Sara Mole, R M Gardiner, Juhani Rapola, Aki Mustonen, Irma Järvelä,

Tópico(s)

RNA regulation and disease

Resumo

Summary Background Batten's disease is the most common progressive encephalopathy of childhood in Western countries. The major mutation is a 1 kb deletion, which is carried by 81% of Batten's disease patients. We report on the use of direct gene analysis in the prenatal diagnosis of this disease. Methods and findings A Finnish woman with a son with Batten's disease came for genetic counselling for her current pregnancy. Electron microscopy of a chorionic villus sample gave suggestive findings. We used PCR to look for the intragenic microsatellite marker D16S298; 96% of Finnish Batten's disease patients carry allele 6 at this marker. The fetus and the affected son both carried the same high-risk genotype, 6/6. Both were homozygous for the 1 kb deletion. The pregnancy was terminated. Electron microscopy of the fetus showed typical Batten's disease changes. Interpretation We have successfully used direct gene analysis in the prenatal diagnosis of Batten's disease.

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